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WT1 germline pathogenic variants drive a spectrum of pediatric kidney predispositions: WA...

Deterministic view of the source YAML entity. Clinical authority remains with the cited source IDs and reviewer sign-off state.

IDBMA-WT1-GERMLINE-WILMS
TypeActionability
Statusreviewed 2026-05-18 | pending_clinical_signoff | actionability review required
DiseasesDIS-WILMS
SourcesSRC-NCCN-PEDIATRIC-SARCOMA

Actionability Facts

BiomarkerBIO-WT1-GERMLINE
VariantWT1 germline pathogenic (WAGR / Denys-Drash / Frasier syndromes)
DiseaseDIS-WILMS
ESCAT tierIIA
Recommended combinationsrenal ultrasound every 3-4 months from diagnosis through age 7-8, urinalysis + blood pressure at each visit (Denys-Drash glomerular surveillance), multi-disciplinary clinic: pediatric oncology + nephrology + endocrinology + genetics, prophylactic gonadectomy in Frasier syndrome (46,XY) — gonadoblastoma prevention, renal function monitoring + proteinuria (Denys-Drash diffuse mesangial sclerosis often presents in infancy), COG / SIOP-RTSG Wilms protocols for any detected nephroblastoma
Evidence summaryWT1 germline pathogenic variants drive a spectrum of pediatric kidney predispositions: WAGR syndrome (11p13 contiguous-gene deletion — Wilms tumor, aniridia, genitourinary anomalies, range of intellectual disability; Wilms risk ~30-50%), Denys-Drash syndrome (missense in zinc- finger domain — pseudohermaphroditism + diffuse mesangial sclerosis + Wilms tumor; risk ~50-90%), and Frasier syndrome (intron-9 splice variants — 46,XY gonadal dysgenesis + focal segmental glomerulosclerosis; gonadoblastoma risk). Confirmed-carrier surveillance protocol (per International Society of Paediatric Oncology / SIOP-RTSG + COG Renal Tumor Committee Consensus / Kalish et al. 2017): renal ultrasound every 3 months from diagnosis through age 7-8 (Wilms incidence peaks before age 5 and falls steeply after age 7), urinalysis at each visit, blood pressure monitoring. Multi-disciplinary involvement: pediatric oncology + nephrology (renal function + proteinuria) + endocrinology (gonadal dysgenesis management) + genetics. Prophylactic gonadectomy is recommended in Frasier syndrome to prevent gonadoblastoma....

Notes

STUB — Wave A+B germline expansion. Linked Indication: none (no WT1- specific Indication exists yet). Two-Clinical-Co-Lead signoff queued. Surveillance is age-bounded: cadence drops markedly after age 7-8 when Wilms incidence falls. Variant location largely predicts syndrome subtype: contiguous-gene deletions → WAGR; zinc-finger missense → Denys- Drash; intron-9 splice variants → Frasier. Other 11p13 contiguous-gene deletion phenotypes (e.g. simultaneous involvement of PAX6) explain aniridia and warrant ophthalmology follow-up.

Used By

No reverse references found in the YAML corpus.